1.1. Aim/Introduction: Odontogenic keratocyst (OKC) is one of the rare odontogenic cyst, commonly affecting the mandible. It has a special mention in the field of oral surgery due to its varied presentation and high recurrence rate. There have been a few cases reported of outcomes of treatment of odontogenic keratocysts. The aim of this report was to illustrate the case of OKC in a patient and to describe the follow-up information and successful treatment of its.